Sleep-related faciomandibular myoclonus: A sleep-related movement disorder different from bruxism.
Identifieur interne : 001D70 ( Ncbi/Checkpoint ); précédent : 001D69; suivant : 001D71Sleep-related faciomandibular myoclonus: A sleep-related movement disorder different from bruxism.
Auteurs : Daniela Loi [Italie] ; Federica Provini ; Roberto Vetrugno ; Roberto D'Angelo ; Anna Zaniboni ; Pasquale MontagnaSource :
- Movement disorders : official journal of the Movement Disorder Society [ 0885-3185 ] ; 2007.
English descriptors
- KwdEn :
- MESH :
- diagnosis : Bruxism, Nocturnal Myoclonus Syndrome.
- methods : Electromyography.
- physiopathology : Facial Muscles, Masticatory Muscles, Nocturnal Myoclonus Syndrome.
- Adult, Diagnosis, Differential, Female, Humans.
Abstract
We describe a 33-year-old man who presented with lip and tongue nibbling and bleeding during sleep. Videopolysomnography revealed myoclonic jerks involving the masticatory and facial muscles recurring mainly during NREM sleep. There was no tonic EMG masticatory activity typical of bruxism. EMG analysis demonstrated the recruitment of V- to VII innervated muscles and, in half of the episodes, also the sternocleidomastoideus. Our patient had sleep-related faciomandibular myoclonus (SFMM) with spontaneous jerks of oromasticatory and cervical muscles, occurring only during sleep. Tooth grinding, temporomandibular joint pain, abnormal tooth mobility, tooth wear, and other dental problems were clinically absent. We propose that, on the basis of the clinical and EMG features, SFMM may be considered a distinct disorder and different from sleep bruxism.
DOI: 10.1002/mds.21661
PubMed: 17657812
Affiliations:
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pubmed:17657812Le document en format XML
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<author><name sortKey="Loi, Daniela" sort="Loi, Daniela" uniqKey="Loi D" first="Daniela" last="Loi">Daniela Loi</name>
<affiliation wicri:level="1"><nlm:affiliation>Department of Neurological Sciences, University of Cagliari, Cagliari, Italy.</nlm:affiliation>
<country xml:lang="fr">Italie</country>
<wicri:regionArea>Department of Neurological Sciences, University of Cagliari, Cagliari</wicri:regionArea>
<wicri:noRegion>Cagliari</wicri:noRegion>
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<author><name sortKey="Provini, Federica" sort="Provini, Federica" uniqKey="Provini F" first="Federica" last="Provini">Federica Provini</name>
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<author><name sortKey="Vetrugno, Roberto" sort="Vetrugno, Roberto" uniqKey="Vetrugno R" first="Roberto" last="Vetrugno">Roberto Vetrugno</name>
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<author><name sortKey="D Angelo, Roberto" sort="D Angelo, Roberto" uniqKey="D Angelo R" first="Roberto" last="D'Angelo">Roberto D'Angelo</name>
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<author><name sortKey="Zaniboni, Anna" sort="Zaniboni, Anna" uniqKey="Zaniboni A" first="Anna" last="Zaniboni">Anna Zaniboni</name>
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<author><name sortKey="Montagna, Pasquale" sort="Montagna, Pasquale" uniqKey="Montagna P" first="Pasquale" last="Montagna">Pasquale Montagna</name>
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<sourceDesc><biblStruct><analytic><title xml:lang="en">Sleep-related faciomandibular myoclonus: A sleep-related movement disorder different from bruxism.</title>
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<author><name sortKey="Provini, Federica" sort="Provini, Federica" uniqKey="Provini F" first="Federica" last="Provini">Federica Provini</name>
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<author><name sortKey="Vetrugno, Roberto" sort="Vetrugno, Roberto" uniqKey="Vetrugno R" first="Roberto" last="Vetrugno">Roberto Vetrugno</name>
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<author><name sortKey="D Angelo, Roberto" sort="D Angelo, Roberto" uniqKey="D Angelo R" first="Roberto" last="D'Angelo">Roberto D'Angelo</name>
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<author><name sortKey="Zaniboni, Anna" sort="Zaniboni, Anna" uniqKey="Zaniboni A" first="Anna" last="Zaniboni">Anna Zaniboni</name>
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<author><name sortKey="Montagna, Pasquale" sort="Montagna, Pasquale" uniqKey="Montagna P" first="Pasquale" last="Montagna">Pasquale Montagna</name>
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<series><title level="j">Movement disorders : official journal of the Movement Disorder Society</title>
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<term>Diagnosis, Differential</term>
<term>Electromyography (methods)</term>
<term>Facial Muscles (physiopathology)</term>
<term>Female</term>
<term>Humans</term>
<term>Masticatory Muscles (physiopathology)</term>
<term>Nocturnal Myoclonus Syndrome (diagnosis)</term>
<term>Nocturnal Myoclonus Syndrome (physiopathology)</term>
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<keywords scheme="MESH" qualifier="diagnosis" xml:lang="en"><term>Bruxism</term>
<term>Nocturnal Myoclonus Syndrome</term>
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<keywords scheme="MESH" qualifier="methods" xml:lang="en"><term>Electromyography</term>
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<keywords scheme="MESH" qualifier="physiopathology" xml:lang="en"><term>Facial Muscles</term>
<term>Masticatory Muscles</term>
<term>Nocturnal Myoclonus Syndrome</term>
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<front><div type="abstract" xml:lang="en">We describe a 33-year-old man who presented with lip and tongue nibbling and bleeding during sleep. Videopolysomnography revealed myoclonic jerks involving the masticatory and facial muscles recurring mainly during NREM sleep. There was no tonic EMG masticatory activity typical of bruxism. EMG analysis demonstrated the recruitment of V- to VII innervated muscles and, in half of the episodes, also the sternocleidomastoideus. Our patient had sleep-related faciomandibular myoclonus (SFMM) with spontaneous jerks of oromasticatory and cervical muscles, occurring only during sleep. Tooth grinding, temporomandibular joint pain, abnormal tooth mobility, tooth wear, and other dental problems were clinically absent. We propose that, on the basis of the clinical and EMG features, SFMM may be considered a distinct disorder and different from sleep bruxism.</div>
</front>
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<affiliations><list><country><li>Italie</li>
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<tree><noCountry><name sortKey="D Angelo, Roberto" sort="D Angelo, Roberto" uniqKey="D Angelo R" first="Roberto" last="D'Angelo">Roberto D'Angelo</name>
<name sortKey="Montagna, Pasquale" sort="Montagna, Pasquale" uniqKey="Montagna P" first="Pasquale" last="Montagna">Pasquale Montagna</name>
<name sortKey="Provini, Federica" sort="Provini, Federica" uniqKey="Provini F" first="Federica" last="Provini">Federica Provini</name>
<name sortKey="Vetrugno, Roberto" sort="Vetrugno, Roberto" uniqKey="Vetrugno R" first="Roberto" last="Vetrugno">Roberto Vetrugno</name>
<name sortKey="Zaniboni, Anna" sort="Zaniboni, Anna" uniqKey="Zaniboni A" first="Anna" last="Zaniboni">Anna Zaniboni</name>
</noCountry>
<country name="Italie"><noRegion><name sortKey="Loi, Daniela" sort="Loi, Daniela" uniqKey="Loi D" first="Daniela" last="Loi">Daniela Loi</name>
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</affiliations>
</record>
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